A Case of Adult Orbital Lymphatic Malformation in the Lacrimal Gland.

Song, Won Seok; Cho, Sung Jin; Choi, Youn Joo

doi:2019.60.4.369

J Korean Ophthalmol Soc > Volume 60(4); 2019 > Article

Case Report

Journal of the Korean Ophthalmological Society 2019;60(4):369-373.
DOI: https://doi.org/10.3341/jkos.2019.60.4.369 Published online April 15, 2019.

A Case of Adult Orbital Lymphatic Malformation in the Lacrimal Gland.

Won Seok Song, Sung Jin Cho, Youn Joo Choi

¹Department of Ophthalmology, Hallym University Kangdong Sacred Heart Hospital, Seoul, Korea. ophdrchoi@gmail.com
²Department of Patholology, Hallym University Kangdong Sacred Heart Hospital, Seoul, Korea.

성인의 눈물샘에서 발생한 안와 림프관 기형 1예

송원석¹⋅조성진²⋅최연주¹

한림대학교 강동성심병원 안과학교실¹, 한림대학교 강동성심병원 병리학교실²

Correspondence: Youn Joo Choi,
Email: ophdrchoi@gmail.com

Received: 4 October 2018 • Revised: 9 November 2018 • Accepted: 23 March 2019

Abstract

PURPOSE
When there is a mass in the superior temporal orbit area, a lacrimal gland tumor should be suspected. We report a rare case of orbital lymphatic malformation that was histologically diagnosed in a patient with typical clinical features of the lacrimal gland. CASE SUMMARY: A 55-year-old female with no underlying disease and no ophthalmic history visited our clinic with a right upper eyelid edema associated with an enlarged painless eyelid mass 1 month prior to her visit. The patient stated that she discovered the mass 1 year previously.The palpebral lobe of the lacrimal gland protruded slightly with congestion of the surrounding conjunctiva. Enhanced computed tomography showed a 3 cm well-defined heterogeneous mass in the right lacrimal gland area and several well-defined round calcifications within the mass. Orbital tissue or bone involvement was not observed. The pleomorphic adenoma of the lacrimal gland was the most clinically suspicious, so complete resection of the mass was performed using lateral orbitotomy. Histopathologically, lymphangioma (lymphatic malformation) originating from the lacrimal gland was diagnosed. CONCLUSIONS: Orbital lymphatic malformation can occur in the lacrimal gland. The present case showed that differential diagnosis can reveal the presence of an adult lacrimal gland tumor.

Key Words: Lacrimal gland tumor;Orbital lymphangioma;Orbital lymphatic malformation